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bioRxiv · 10.64898/2026.07.15.738809

Scalable single-cell isoform profiling with sequencing-by-expansion

Abstract

Single-cell RNA sequencing has transformed our understanding of cellular systems, yet the reliance on short-read sequencing restricts analysis to gene-level quantification and obscures the immense biological diversity generated by alternative splicing. While long-read sequencing technologies can capture full-length RNA and resolve transcript isoforms, current platforms remain constrained by throughput and high per-base costs, rendering them impractical for modern million-cell applications. To address this critical limitation, we developed and optimized sequencing-by-expansion (SBX) chemistry for high-throughput single-cell RNA isoform profiling. Integrated within the AXELIOS 1 sequencing platform, SBX employs a unique biochemical conversion process that transforms complementary DNA into expanded surrogate high signal-to-noise polymers called Xpandomers which are sequenced via translocation through a dense nanopore array yielding over 9.5 billion reads in a two-hour run. To leverage this unique data type for long-read single-cell RNA isoform sequencing, we developed the Consensus UMI Deduplication using Longest Length (CUDLL) algorithm, which computationally consolidates variable-length raw SBX reads into single, high-fidelity consensus reads, elevating sequence accuracy to 99.83% and maximizing per transcript read length. We demonstrate that this consensus approach successfully captures the vast isoform diversity of single-cell libraries and enables the accurate measure of differential isoform expression across distinct cell types in peripheral blood mononuclear cells. Furthermore, SBX coupled with CUDLL efficiently resolves T-cell and B-cell receptor clonotypes directly from whole-transcriptome libraries without the need for VDJ-specific target enrichment. Ultimately, this work establishes SBX and the AXELIOS 1 as a transformative platform for high-scale single-cell isoform sequencing.

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BibTeXRIS

Georgescu, C. H., Al-Eryani, G., Brookhart, A., Chandrasekar, J., Yaung, S. J., Rogers-Peckham, M., Freer, M., Kartje, M. E., Yu, H., Khorgade, A., Yang, C., McGee, L., Berg, K., Cech, C., Barrett, S., Arryman, A., Bartlett, D. A., Slamin, A., Low, S., Dubinsky, D., Cipicchio, M., Hacohen, N., Lehmann, T., Lennon, N. J., Popic, V., Zhao, C., Prindle, M., Mannion, J., Nabavi, M., Haas, B. J., Kokoris, M., AlKhafaji, A. M.. 2026-07-21. Scalable single-cell isoform profiling with sequencing-by-expansion. https://doi.org/10.64898/2026.07.15.738809

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