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bioRxiv · 10.64898/2026.01.22.701028

dirCLIP profiles variant-specific RNA-protein interactions via nanopore long-read sequencing

Abstract

RNA binding proteins (RBPs) control gene expression through their activities in essentially all processing steps of coding and noncoding RNAs and are dysregulated in disease. With >95% of human multi-exon genes undergoing alternative splicing, the inability to assign RBP sites to distinct RNA variants fundamentally limits our understanding of RNA regulation. We present dirCLIP, a method combining UV crosslinking and immunoprecipitation (CLIP) with amplification-free direct nanopore long-read sequencing preserving full-length transcripts. dirCLIP employs two complementary strategies: direct RNA sequencing detecting amino acid adduct-induced perturbations in current signals and direct cDNA sequencing capturing binding sites as mutations. Benchmarking dirCLIP with SRSF3 demonstrated >75% concordance with short-read-based data, revealed isoform-selective RNA binding and enabled detection of co-occurring binding sites in single RNA molecules. Application to the noncanonical RBP HMGA1 uncovered new AT-hook mediated RNA variant-specific interactions. dirCLIP fundamentally transforms our ability to interrogate RNA regulation of distinct isoforms and transcript variants with direct implications to disease mechanisms and development of RNA therapeutics.

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BibTeXRIS

Bahrudeen, M., Scaravilli, M., Zahir, Z., Woodward, K., Ahola, T., Ratnadiwakara, M., Kaslin, J., Loughlin, F., Shirokikh, N. E., Anko, M.-L.. 2026-01-22. dirCLIP profiles variant-specific RNA-protein interactions via nanopore long-read sequencing. https://doi.org/10.64898/2026.01.22.701028

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