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bioRxiv · 10.1101/2025.09.09.675030

CD19xCD3 bispecific T cell engager treatment induces remission in experimental pemphigoid disease

Abstract

Pemphigoid diseases (PDs) are autoimmune disorders marked by autoantibodies (Aab) against skin and mucous membrane proteins, causing muco-cutaneous blistering in predominantly elderly patients. Since current therapeutics are often insufficient, PDs impose a significant morbidity and mortality burden. CD19xCD3 bispecific T cell engagers (TCEs) - originally developed for B cell malignancies - have shown promise in treatment-refractory autoimmune diseases like systemic sclerosis and rheumatoid arthritis. To explore their potential in PDs, we tested a murine CD19xCD3 TCE in a mouse model of epidermolysis bullosa acquisita (EBA), a prototypical PD. The TCE selectively depleted B cells in blood and bone marrow, but not spleen, of healthy mice. Mice with clinically manifest immunization-induced EBA were randomized to receive either the CD19xCD3 TCE or control treatment upon reaching a predefined disease severity. After 13 weeks, 45% of TCE-treated mice achieved remission, versus 23% of controls. This improvement correlated with reduced antigen-specific B cells, though total and antigen-specific IgG levels were unchanged. These findings suggest that CD19xCD3 TCE preferentially target autoreactive B cells and may be effective at lower doses than those used in oncology. Our data support the potential of CD19xCD3 bispecific T cell engagers as a therapeutic strategy for PDs. eTOC SynopsisGross, Jochimsen, Drager and colleagues demonstrate that CD19xCD3 bispecific T cell engagers, can selectively target autoreactive B cells and induce remission in a mouse model of pemphigoid disease, highlighting their potential as a novel therapeutic strategy for autoimmune blistering disorders.

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BibTeXRIS

Gross, N., Jochimsen, A., Draeger, S., Theocharis, T., Recke, A., van Beek, N., Schmidt-Jimenez, L., Krohn, S., Klausz, K., Bieber, K., Ludwig, R. J., Peipp, M.. 2025-09-12. CD19xCD3 bispecific T cell engager treatment induces remission in experimental pemphigoid disease. https://doi.org/10.1101/2025.09.09.675030

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