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Biology subjects

Mendelson, M. M.

Publications and source records attributed to Mendelson, M. M..

2 recordsLinked to original sources

Analysis of reproductive traits associated with lipoprotein(a) deficiency in participants from the Pakistan Genome Resource

Aims. Lipoprotein(a) [Lp(a)] is a genetically determined, independent risk factor for atherosclerotic cardiovascular disease, driving development of LPA-targeting therapies that markedly lower circulating Lp(a). Because LPA?the gene encoding apolipoprotein(a)?is absent in most model organisms, preclinical studies have limited value for assessing effects such as reproductive safety. Therefore, naturally occurring human LPA ?knockouts? were analyzed to evaluate reproductive outcomes of on-target Lp(a) lowering. Methods and Results. Individuals carrying high-confidence LPA loss-of-function (LoF) variants which reduce Lp(a) in a gene-dosage?dependent manner within the Pakistan Genome Resource were identified. LoF variants showed no depletion of homozygotes relative to Hardy?Weinberg expectations. LPA LoF associations with fertility-related traits (ever having a child and number of children) under additive and recessive models were assessed using regenie-based burden testing, including sex-stratified analyses, and no significant associations were observed. A recall-by-genotype study of female LoF homozygotes alongside heterozygous and non-carrier family member controls was performed, surveying reproductive histories and offspring outcomes. Across 107 pregnancies and 87 children in 19 homozygous LoF women, rates of miscarriage, maternal complications (including preeclampsia, hypertension, and gestational diabetes), delivery complications, neonatal intensive care admission, birth defects, and child health problems were comparable across genotypes with no statistically significant genotype?outcome associations. Conclusions. These genetic and by-genotype analyses indicate that complete lifelong LPA deficiency due to high-confidence LPA loss-of-function variants is not associated with overt adverse maternal fertility, pregnancy or child health outcomes. These findings offer human genetic reassurance regarding reproductive and developmental safety in the context of sustained Lp(a)-lowering, with implications for long-term therapies targeting Lp(a).

genetics↗

Transgelin: A New Gene Involved in LDL Endocytosis Identified by a Genome-wide CRISPR-Cas9 Screen

To identify new genes involved in the cellular uptake of low-density lipoprotein (LDL), we applied a novel whole genome CRISPR/Cas9 knockout-screen on HepG2 cell lines. We identified TAGLN (transgelin), an actin-binding protein, as a new gene involved in LDL endocytosis. In silico validation demonstrated that genetically predicted differences in expression of TAGLN in human populations were associated with plasma lipids (triglycerides, total cholesterol, HDL, and LDL cholesterol) in the Global Lipids Genetics Consortium and lipid-related phenotypes in the UK Biobank. Decreased cellular LDL uptake observed in TAGLN-knockout cells due to decreased LDL receptor internalization, led to alterations in cellular cholesterol content and compensatory changes in cholesterol biosynthesis. Transgelin was also shown to be involved in the actin-dependent phase of clathrin-mediated endocytosis of other cargo besides LDL. The identification of novel genes involved in LDL uptake may improve the diagnosis of hypercholesterolemia and provide future therapeutic targets for the prevention of cardiovascular disease.

cell biology↗