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Biology subjects

Garaycoechea, J. I.

Publications and source records attributed to Garaycoechea, J. I..

2 recordsLinked to original sources

Mutagenic bypass of uracil-derived abasic sites underlies the SBS17 mutational signature

Understanding how mutations arise is central to predicting and preventing cancer, yet most of the mutational signatures found in cancer genomes still have no known mechanistic cause. Among these, single-base-substitution signature 17 (SBS17) is the dominant mutational process in gastric and oesophageal adenocarcinoma. SBS17 has been linked to oxidative damage and to the chemotherapeutic agent 5-fluorouracil (5-FU), but the molecular events that generate it are unknown. Here we demonstrate that SBS17 causes driver mutations in gastrointestinal cancer. We then combine genetics in cell lines and organoids with whole-genome sequencing to define the mechanistic aetiology of SBS17 mutagenesis. We disprove the prevailing oxidative damage hypothesis and instead show that SBS17 arises through the misincorporation of dUTP during DNA replication, followed by uracil excision by the glycosylase UNG and mutagenic bypass of the resulting abasic (AP) sites by the translesion synthesis machinery. Importantly, we reveal that the same mechanism underlies both spontaneous and chemotherapy-induced mutations. Together, our results resolve the origin of gastric mutagenesis, opening therapeutic avenues for curbing ongoing mutagenesis, tumour evolution and drug resistance in gastrointestinal cancers.

molecular biology↗

Mechanistically distinct BER processes are essential for the tolerance of exogenous 5hm-dC and enzymatic oxidative demethylation

Epigenetic information is transmitted through covalent DNA modifications that regulate chromatin structure and gene expression. 5-Hydroxymethylcytosine (5hmC) is a key epigenetic intermediate generated during TET-mediated oxidative demethylation of 5-methylcytosine. Whether 5hmC itself is intrinsically genotoxic remains unclear. Here, we combine genome-wide CRISPR loss-of-function screens, isogenic knockouts and mass spectrometry to systematically compare the cellular consequences of exogenous 5-hydroxymethyl-2'-cytidine (5hm-dC) exposure and endogenous oxidative demethylation in mammalian cells. We find that exogenous 5hm-dC causes toxicity, mediated by deamination to 5-hydroxymethyl-2'-deoxyuridine (5hm-dU), followed by excision by the glycosylase SMUG1, which generates base excision repair (BER) intermediates that compromise cell viability. In contrast, toxicity associated with enzymatic oxidative demethylation is primarily driven by TDG-dependent excision of oxidized methylcytosine derivatives. Despite these distinct initiating events, both genotoxins converge on a critical requirement for DNA polymerase {beta} (POL{beta}), indicating that efficient BER completion is essential to mitigate cytotoxic repair intermediates.

molecular biology↗