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Gallagher, R. L.

Publications and source records attributed to Gallagher, R. L..

2 recordsLinked to original sources

A high throughput system reveals distinct segmentation clock phase responses in hiPSC-derived organoids

During somitogenesis, the vertebrate body axis segments into transient periodic structures known as somites. Somite formation is regulated by a multicellular molecular oscillator known as the segmentation clock. Recent advances in human induced pluripotent stem cell (hiPSC) culture have shown that hiPSC-derived somitogenesis organoids (somitoids) exhibit segmentation clock oscillations and can be produced at scale, making them an excellent model system for high throughput investigation of the mechanisms underpinning the segmentation clock. However, somitoids interact both biochemically and mechanically, and accurate high-throughput sampling of segmentation clock phases is required to exploit this system effectively. Here we address these challenges using an image-based, high-content screening workflow. Individual hiPSC-derived somitoids carrying a segmentation clock reporter are cultured in 384-well plates, and a programmable feeding schedule is used to initiate oscillations that are monitored using fluorescence microscopy. We develop an automated pipeline for image segmentation and data analysis, represent oscillations using a compact set of parameters, and construct predictive mathematical models to interpret data. We find that: (i) a staggered feeding schedule that sequentially initiates oscillations yields large numbers of somitoids at defined stages of the segmentation clock cycle; (ii) media exchange in established oscillations induces a Type 0-like phase response, resetting the segmentation clock to a state characterised by low NOTCH pathway transcription; and (iii) control wells in media exchange experiments exhibit a Type 1 phase response in which the segmentation clock is delayed non-uniformly across the cycle. Using a mathematical model of segmentation clock dynamics along the anterior-posterior axis, we show that periodic activation of a Type 1 phase response could segment a continuous phase gradient -- an insight with potential implications for the determination of somite boundaries in vivo. IMPORTANTO_LIManuscripts submitted to Review Commons are peer reviewed in a journal-agnostic way. C_LIO_LIUpon transfer of the peer reviewed preprint to a journal, the referee reports will be available in full to the handling editor. C_LIO_LIThe identity of the referees will NOT be communicated to the authors unless the reviewers choose to sign their report. C_LIO_LIThe identity of the referee will be confidentially disclosed to any affiliate journals to which the manuscript is transferred. C_LI GUIDELINESO_LIFor reviewers: https://www.reviewcommons.org/reviewers C_LIO_LIFor authors: https://www.reviewcommons.org/authors C_LI CONTACTThe Review Commons office can be contacted directly at: office@reviewcommons.org

developmental biology↗

NOTCH1 S2513 is critical for the regulation of NICD levels impacting the segmentation clock in hiPSC-derived PSM cells and somitoids

The segmentation clock is a molecular oscillator that regulates the timing of somite formation in the developing vertebrate embryo. NOTCH signalling is one of the key pathways required for proper functioning of the segmentation clock. Aberrant NOTCH signalling results in developmental abnormalities such as congenital scoliosis as well as diseases such as T-cell acute lymphoblastic lymphoma (T-ALL). In this study we analyse the effects of a mutation detected in T-ALL patients on somitogenesis using human iPS derived PSM cells and somitoids. Mutation of NOTCH1 Serine 2513 into Alanine compromises the interaction of Notch intracellular domain (NICD) with the F-box protein FBXW7 and consequently increases NICD stability and NICD levels in PSM cells. Moreover, the mutation impairs several aspects of clock gene oscillations and restricts the ability of somitoids to polarise, elongate and form paired somites. The data suggest a mechanism by which post-translational modification of a key segmentation clock component plays a crucial role in vertebrate axis segmentation.

developmental biology↗