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Carignano, C.

Publications and source records attributed to Carignano, C..

2 recordsLinked to original sources

Insights into early cochlear damage induced by potassium channel deficiency

Hearing loss (HL) is the most common sensory disorder, caused by genetic mutations and acquired factors like presbycusis and noise exposure. A critical factor in HL development is the dysfunction of potassium (K+) channels, essential for sensory cell function in the organ of Corti (OC). Inner and outer hair cells (IHCs and OHCs) convert sound into electrical signals, while supporting cells (SCs) maintain ionic and structural balance. KCNQ4 channels, located in the basal membrane of OHCs, regulate K+ efflux. Mutations in KCNQ4 are linked to progressive HL (DFNA2), noise-induced hearing loss, and presbycusis, leading to K+ accumulation, cellular stress, and OHC death. Gene editing or pharmacological activation of KCNQ4 has shown potential in partially preventing HL in mouse models. In this study, we demonstrate KCNQ4 deletion disrupts the localization of key proteins like prestin and BK channels, alters OHC organization, and induces apoptosis in sensory and SC. Spiral ganglion neurons (SGNs) also degenerate over time. Despite these structural changes, noise exposure does not exacerbate OHC damage in our KCNQ4-deficient model. This highlights KCNQ4s role in maintaining ion homeostasis and cochlear function, as its absence triggers widespread dysfunction in the OC. The present study demonstrates that disruptions in a single cell type can have a cascade effect on overall cochlear health. Understanding the molecular and cellular consequences of KCNQ4 mutations is crucial for developing targeted therapies to mitigate progressive HL caused by genetic and environmental factors. HighlightsO_LIHearing function is altered in KCNQ4 KO animals from young ages. C_LIO_LIInner hair cells show structural alterations before their death. C_LIO_LIKCNQ4 absence impairs membrane localization of key functional proteins. C_LIO_LIHair cell and neuron loss is mediated by apoptosis. C_LIO_LISupporting cells and satellite cells also contribute to tissue degeneration in KCNQ4 KO animals C_LIO_LINoise exposure does not exacerbate hair cell damage in KCNQ4-KO mice. C_LI

neuroscience↗

Time-course Pattern of Cell Degeneration in a Mouse with Cochlear Hair Cell Impaired Potassium Outflow

HIGHLIGHTSO_LIKCNQ4 knock-out mouse shows hair cells and spiral ganglion neuron degeneration.\nC_LIO_LIInner hair cells and spiral ganglion neuron loss begin 30 weeks later than outer hair cells in Kcnq4-/- mice.\nC_LIO_LIInner hair cell loss kinetic is faster than that of outer hair cells in cochlear basal turn in Kcnq4-/-.\nC_LIO_LIOuter hair cells from Kcnq4-/- mice degenerate slower in apical than in basal turn.\nC_LIO_LIKcnq4 knock-out allele expressed in C3H/HeJ strain reproduces the two phases of DFNA2 hearing loss.\nC_LI\n\nGRAPHICAL ABSTRACT\n\nO_FIG O_LINKSMALLFIG WIDTH=200 HEIGHT=78 SRC=\"FIGDIR/small/469676_ufig1.gif\" ALT=\"Figure 1\">\nView larger version (31K):\norg.highwire.dtl.DTLVardef@1bdff20org.highwire.dtl.DTLVardef@b8cc51org.highwire.dtl.DTLVardef@6deeb9org.highwire.dtl.DTLVardef@153f381_HPS_FORMAT_FIGEXP M_FIG C_FIG

neuroscience↗